Retinoic-acid-orphan-receptor-C inhibition suppresses Th17 cells and induces thymic aberrations.

نویسندگان

  • Christine Guntermann
  • Alessandro Piaia
  • Marie-Laure Hamel
  • Diethilde Theil
  • Tina Rubic-Schneider
  • Alberto Del Rio-Espinola
  • Linda Dong
  • Andreas Billich
  • Klemens Kaupmann
  • Janet Dawson
  • Klemens Hoegenauer
  • David Orain
  • Samuel Hintermann
  • Rowan Stringer
  • Dhavalkumar D Patel
  • Arno Doelemeyer
  • Mark Deurinck
  • Jens Schümann
چکیده

Retinoic-acid-orphan-receptor-C (RORC) is a master regulator of Th17 cells, which are pathogenic in several autoimmune diseases. Genetic Rorc deficiency in mice, while preventing autoimmunity, causes early lethality due to metastatic thymic T cell lymphomas. We sought to determine whether pharmacological RORC inhibition could be an effective and safe therapy for autoimmune diseases by evaluating its effects on Th17 cell functions and intrathymic T cell development. RORC inhibitors effectively inhibited Th17 differentiation and IL-17A production, and delayed-type hypersensitivity reactions. In vitro, RORC inhibitors induced apoptosis, as well as Bcl2l1 and BCL2L1 mRNA downregulation, in mouse and nonhuman primate thymocytes, respectively. Chronic, 13-week RORC inhibitor treatment in rats caused progressive thymic alterations in all analyzed rats similar to those in Rorc-deficient mice prior to T cell lymphoma development. One rat developed thymic cortical hyperplasia with preneoplastic features, including increased mitosis and reduced IKAROS expression, albeit without skewed T cell clonality. In summary, pharmacological inhibition of RORC not only blocks Th17 cell development and related cytokine production, but also recapitulates thymic aberrations seen in Rorc-deficient mice. While RORC inhibition may offer an effective therapeutic principle for Th17-mediated diseases, T cell lymphoma with chronic therapy remains an apparent risk.

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عنوان ژورنال:
  • JCI insight

دوره 2 5  شماره 

صفحات  -

تاریخ انتشار 2017